Evaluating a new gene therapy for Retinitis Pigmentosa

A Phase 1/2a, Open-Label, Non-Randomized, Dose-Escalation Study to Evaluate the Safety and Tolerability of GS030 in Subjects With Retinitis Pigmentosa

Phase1; Phase2 Interventional GenSight Biologics · NCT03326336

This study is testing a new gene therapy for people with Retinitis Pigmentosa to see if it is safe and how well it works when given through an eye injection along with a special light device.

Quick facts

PhasePhase1; Phase2
Study typeInterventional
Enrollment15 (estimated)
Ages18 Years to 75 Years
SexAll
SponsorGenSight Biologics Industry-sponsored
Locations3 sites (Pittsburgh, Pennsylvania and 2 other locations)
Trial IDNCT03326336 on ClinicalTrials.gov

What this trial studies

This study aims to assess the safety and tolerability of a gene therapy called GS030-DP, which is administered through a single intravitreal injection. Participants will also use a medical device known as GS030-MD, which provides repeated light stimulation. The study involves dose-escalation to determine the optimal dosage for patients diagnosed with non-syndromic Retinitis Pigmentosa. It includes adults aged 18 to 75 with specific visual acuity and retinal measurements.

Who should consider this trial

Good fit: Ideal candidates are adults aged 18 to 75 with a confirmed diagnosis of non-syndromic Retinitis Pigmentosa and specific visual acuity criteria.

Not a fit: Patients who have previously received gene therapy or undergone significant ocular surgery within the last three months may not benefit from this study.

Why it matters

Potential benefit: If successful, this therapy could improve vision and quality of life for patients suffering from Retinitis Pigmentosa.

How similar studies have performed: While gene therapies for retinal diseases are emerging, this specific approach using GS030 has not been widely tested in prior studies.

Eligibility criteria

Show full inclusion / exclusion criteria
Main selection criteria:

* Age ≥18 years to ≤75 years at the time of ICF signature.
* Diagnosis of non-syndromic RP defined as:

  * Clinical diagnosis of non-syndromic RP based on history, mid-peripheral visual dysfunction, and fundoscopic appearance.
  * Diagnosis of non-syndromic RP is confirmed on full-field ERG
* Visual acuity:

  * Visual acuity in the dose-escalation cohorts of no better LP.
  * Visual acuity in the extension cohort of no better than CF pending review of dose-escalation cohort data by the DSMB.
* Relatively preserved ganglion cell layer volume and retinal nerve fiber layer thickness, as measured with spectral domain optical coherence tomography (SD-OCT).
* Interpupillary distance of ≥51 mm and ≤72 mm.
* Refractive error of the study eye between -6 diopters and +6 diopters.

Main non-selection criteria

* Prior receipt of any gene therapy.
* Subjects who have undergone significant ocular surgery (per investigator determination) within 3 months prior to Visit 1.
* Presence of narrow iridocorneal angles contraindicating pupillary dilation.
* Presence of disorders of the ocular media which interfere with visual acuity and other ocular assessments, including SD-OCT, during the study period.
* Presence of any systemic or ocular diseases, or pathologies, other than non-syndromic RP, or their associated therapies, that can cause or have the potential to cause vision loss.
* Prior vitrectomy or vitreomacular surgery.
* Presence of vitreo-macular adhesion or traction, epiretinal membrane, macular pucker and macular hole, evident by ophthalmoscopy and/or by SD-OCT examinations and assessed by the investigator to significantly affect central vision.
* Current evidence of retinal detachment assessed by the investigator to significantly affect central vision.
* Active ocular inflammation or recurrent history of idiopathic or autoimmune associated uveitis.
* Presence of an Active Implantable Medical Device.
* Subjects who have undergone thermal laser procedure to the retina within 3 months of trial entry, or any prior thermal laser procedure to the macular region.

Where this trial is running

Pittsburgh, Pennsylvania and 2 other locations

Study contacts

How to participate

  1. Review the eligibility criteria above with your treating physician.
  2. Visit the official trial page on ClinicalTrials.gov for the most current contact information and recruitment status.
  3. Contact the listed study coordinator or principal investigator to request pre-screening. Pre-screening is free and never obligates you to enroll.
Conditions Non-syndromic Retinitis PigmentosaEye DiseasesHereditary Eye DiseasesRetinal degenerationInherited retinal diseasesRod & cone dystrophiesRetinitis PigmentosaGene Therapy
Last reviewed 2026-06-13 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.