Effects of bisphosphonates on hearing loss in osteogenesis imperfecta

Effects of Bisphosphonates on OI-Related Hearing Loss: A Pilot Study

PHASE4 · Hospital for Special Surgery, New York · NCT04152551

This study is testing if a medication called bisphosphonates can help adults with Osteogenesis Imperfecta type I who have hearing loss.

Quick facts

PhasePHASE4
Study typeInterventional
Enrollment100 (estimated)
Ages6 Years to 100 Years
SexAll
SponsorHospital for Special Surgery, New York (other)
Locations1 site (New York, New York)
Trial IDNCT04152551 on ClinicalTrials.gov

What this trial studies

This study investigates the impact of bisphosphonate treatment on hearing loss associated with Osteogenesis Imperfecta (OI) type I. It aims to enroll 50 adults, with half receiving bisphosphonates and the other half serving as a control group. Participants must have a diagnosis of OI type I and at least mild hearing loss. The study will assess the effectiveness of bisphosphonates, which have shown promise in treating similar hearing loss conditions.

Who should consider this trial

Good fit: Ideal candidates include adults aged 18-100 with a diagnosis of OI type I and at least mild hearing loss.

Not a fit: Patients with a family history of hearing loss unrelated to OI or those who are pregnant may not benefit from this study.

Why it matters

Potential benefit: If successful, this treatment could improve hearing outcomes for patients with Osteogenesis Imperfecta-related hearing loss.

How similar studies have performed: Previous studies have shown bisphosphonates to be effective in treating otosclerosis, suggesting potential success for this approach in OI-related hearing loss.

Eligibility criteria

Show full inclusion / exclusion criteria
Inclusion Criteria (Adult Treatment Arm):

* Diagnosis of OI type I
* Diagnosis of at least mild hearing loss (\>20dB pure tone average) by audiogram testing
* 18+
* Vitamin D level \> 30

Inclusion Criteria (Adult Control Arm):

* Diagnosis of OI type I

Inclusion Criteria (Child Observational Bisphosphonate Arm)

* Diagnosis of OI
* Age 6-17 years
* Currently receiving bisphosphonate treatment as standard of care

Inclusion Criteria (Child Observational No Treatment Arm)

* Diagnosis of OI
* Age 6-17 years
* NOT receiving bisphosphonate treatment and will not receive bisphosphonate treatment for the duration of the study

Exclusion Criteria (ALL ARMS):

* Family history of hearing-loss (not related to OI or occupational hearing loss)
* Pregnancy

Where this trial is running

New York, New York

Study contacts

How to participate

  1. Review the eligibility criteria above with your treating physician.
  2. Visit the official trial page on ClinicalTrials.gov for the most current contact information and recruitment status.
  3. Contact the listed study coordinator or principal investigator to request pre-screening. Pre-screening is free and never obligates you to enroll.

View on ClinicalTrials.gov →

Conditions: Osteogenesis Imperfecta, hearing loss, bisphosphonate, skeletal dysplasia, brittle bone disorder, osteogenesis imperfecta, OI

Last reviewed 2026-05-15 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.