Injecting AAVB-081 to treat Usher Syndrome Type IB

A Phase 1/2 Multicenter, Open-label, Dose Escalation, Safety and Efficacy Study of Subretinal Administration of Dual AAV8.MYO7A, AAVB-081 in Subjects With Usher Syndrome Type IB (USH1B) Retinitis Pigmentosa

PHASE1; PHASE2 · AAVantgarde Bio Srl · NCT06591793

This study is testing a new injection for people with Usher Syndrome Type IB to see if it is safe and helps improve their vision.

Quick facts

PhasePHASE1; PHASE2
Study typeInterventional
Enrollment15 (estimated)
Ages18 Years to 50 Years
SexAll
SponsorAAVantgarde Bio Srl (industry)
Locations3 sites (Naples and 2 other locations)
Trial IDNCT06591793 on ClinicalTrials.gov

What this trial studies

This study evaluates the safety and tolerability of a single subretinal injection of AAVB-081 in patients with Usher Syndrome Type IB, specifically those with retinitis pigmentosa caused by a MYO7A gene mutation. The study aims to assess the initial efficacy of the treatment following administration. Participants will be monitored for any adverse effects and the overall response to the therapy.

Who should consider this trial

Good fit: Ideal candidates are individuals diagnosed with Usher Syndrome Type IB due to a MYO7A mutation.

Not a fit: Patients with complicating ocular or systemic diseases or those who have recently participated in other gene therapy trials may not benefit from this study.

Why it matters

Potential benefit: If successful, this treatment could improve vision and quality of life for patients with Usher Syndrome Type IB.

How similar studies have performed: Other studies involving gene therapy for retinal diseases have shown promising results, indicating potential for success in this approach.

Eligibility criteria

Show full inclusion / exclusion criteria
Inclusion Criteria:

* Molecular diagnosis of USB1B due to MYO7A mutation
* Willingness to adhere to protocol per informed consent

Exclusion Criteria:

* Unwillingness to meet the requirements of the study
* Participation in a clinical study with an Investigation Product in the past 6 months
* Previous participation in another Gene Therapy trial
* Any condition that would preclude subretinal surgery
* Complicating ocular and/or systemic diseases

Where this trial is running

Naples and 2 other locations

Study contacts

How to participate

  1. Review the eligibility criteria above with your treating physician.
  2. Visit the official trial page on ClinicalTrials.gov for the most current contact information and recruitment status.
  3. Contact the listed study coordinator or principal investigator to request pre-screening. Pre-screening is free and never obligates you to enroll.

View on ClinicalTrials.gov →

Conditions: Usher Syndrome, Type 1B, Usher Syndrome, MYO7A, USH1B, Retinitis Pigmentosa

Last reviewed 2026-05-15 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.