Gene therapy for retinal dystrophy caused by RPE65 mutations

A Multi-center, Open-label, Dose-escalation Phase I/II Clinical Study to Evaluate the Safety, Tolerability and Efficacy of FT-001 Administered Via Subretinal Injection in Subjects With Biallelic RPE65 Mutation-associated Retinal Dystrophy

Phase1; Phase2 Interventional Frontera Therapeutics · NCT05858983

This study is testing a new gene therapy called FT-001 to see if it can improve vision in people with retinal dystrophy caused by RPE65 mutations.

Quick facts

PhasePhase1; Phase2
Study typeInterventional
Enrollment9 (estimated)
Ages8 Years to 45 Years
SexAll
SponsorFrontera Therapeutics Industry-sponsored
Locations1 site (Beijing, Beijing Municipality)
Trial IDNCT05858983 on ClinicalTrials.gov

What this trial studies

This clinical trial evaluates the safety, tolerability, and efficacy of a gene therapy called FT-001 administered subretinally in patients with biallelic RPE65 mutation-associated retinal dystrophy. It is a multi-center, open-label study that will assess various outcomes, including visual acuity and potential side effects, over a monitoring period of five years. The trial includes different dosage levels of FT-001 to determine the optimal treatment approach.

Who should consider this trial

Good fit: Ideal candidates are individuals aged 8-45 years with a clinical diagnosis of biallelic RPE65 mutation-associated retinal dystrophy.

Not a fit: Patients with other eye diseases or systemic conditions that could affect vision are unlikely to benefit from this study.

Why it matters

Potential benefit: If successful, this therapy could significantly improve vision and quality of life for patients with this specific genetic condition.

How similar studies have performed: Previous studies on gene therapy for retinal dystrophies have shown promising results, indicating potential for success in this approach.

Eligibility criteria

Show full inclusion / exclusion criteria
Inclusion Criteria:

1. Subjects who are able to understand and sign the ICF
2. Female or male aged 8-45 years old when signing the ICF
3. Clinically diagnosed with biallelic RPE65 mutation-associated retinal dystrophy

Exclusion Criteria:

1. Other interfering eye diseases
2. Presence of any systemic or ocular disease that can cause or likely to cause vision loss
3. There is evidence of obviously uncontrolled concomitant diseases
4. Known to have active or suspected autoimmune diseases
5. With active systemic infection under treatment
6. Pregnant or lactating women
7. Other conditions unsuitable for the study as determined by the investigator

Where this trial is running

Beijing, Beijing Municipality

Study contacts

How to participate

  1. Review the eligibility criteria above with your treating physician.
  2. Visit the official trial page on ClinicalTrials.gov for the most current contact information and recruitment status.
  3. Contact the listed study coordinator or principal investigator to request pre-screening. Pre-screening is free and never obligates you to enroll.
Conditions Biallelic RPE65 Mutation-associated Retinal DystrophyFT-001
Last reviewed 2026-06-09 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.