Understanding how cell powerhouses cause inflammation in a childhood brain disease

The Mitochondrion-STING Axis in An Early Childhood Onset Neurodegenerative Disease

NIH-funded research Ut Southwestern Medical Center · NIH-11123425

This research explores how problems with cell powerhouses, called mitochondria, lead to inflammation in children with a severe brain condition called NGLY1 deficiency.

Quick facts

Grant typeR01 grant
Study typeNIH-funded research
Funding institutionUt Southwestern Medical Center NIH-funded
Lab location1 site (Dallas, United States)
Project IDNIH-11123425 on NIH RePORTER

What this research studies

Our cells' powerhouses, mitochondria, can trigger inflammation when damaged, similar to how the body reacts to bacteria. We've found that a missing protein, NGLY1, causes mitochondrial damage and activates a strong inflammatory response in the brain. This project aims to uncover exactly how this inflammation contributes to the severe brain problems seen in children with NGLY1 deficiency, a condition currently without a cure. We will look at specific brain cells and their internal signals to understand this process better. Ultimately, we hope to test new treatments that target this inflammatory pathway.

Who could benefit from this research

Good fit: Patients with NGLY1 deficiency or similar early-onset neurodegenerative conditions, particularly those experiencing severe coordination and motor function issues, could potentially benefit from future therapies developed from this research.

Not a fit: Patients whose conditions are not related to mitochondrial damage or the specific inflammatory pathway being studied may not directly benefit from this particular research.

Why it matters

Potential benefit: If successful, this work could reveal new ways to treat NGLY1 deficiency and potentially other brain diseases by targeting the inflammation caused by damaged mitochondria.

How similar studies have performed: Our team has already shown that NGLY1 deficiency causes mitochondrial damage and activates this inflammatory pathway, providing a strong foundation for this deeper investigation into the disease mechanism.

Where this research is happening

Dallas, United States

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.
Conditions Amyotrophic Lateral Sclerosis Motor Neuron Disease
Last reviewed 2026-06-13 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.