Understanding how a specific protein affects gene activation in development and disease

5-methylcytosine oxidation in development and disease

NIH-funded research Van Andel Research Institute · NIH-11061906

This study is looking at how a protein called SMCHD1 affects gene activity related to development and diseases like facioscapulohumeral muscular dystrophy (FSHD), using mouse and human stem cells to understand what happens when this protein is missing.

Quick facts

Grant typeR01 grant
Study typeNIH-funded research
Funding institutionVan Andel Research Institute NIH-funded
Lab location1 site (Grand Rapids, United States)
Project IDNIH-11061906 on NIH RePORTER

What this research studies

This research investigates the role of a protein called SMCHD1 in regulating the oxidation of 5-methylcytosine, a process that can activate genes involved in embryonic development and diseases like facioscapulohumeral muscular dystrophy (FSHD). By using mouse embryonic stem cells and human induced pluripotent stem cells, the researchers aim to uncover how the absence of SMCHD1 alters gene activity and contributes to disease. The study will explore the mechanisms behind TET proteins, which are crucial for gene activation, and how they are influenced by SMCHD1. This research could provide insights into the fundamental processes of gene regulation and its implications for various health conditions.

Who could benefit from this research

Good fit: Ideal candidates for this research are individuals affected by facioscapulohumeral muscular dystrophy or related genetic conditions.

Not a fit: Patients with conditions unrelated to gene activation or those not affected by FSHD may not benefit from this research.

Why it matters

Potential benefit: If successful, this research could lead to new therapeutic strategies for diseases linked to gene activation, such as FSHD.

How similar studies have performed: Previous research has shown promising results in understanding gene regulation through similar mechanisms, indicating potential for success in this area.

Where this research is happening

Grand Rapids, United States

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.
Last reviewed 2026-06-13 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.