Understanding how a protein affects muscle function using zebrafish.

Skeletal Myosin-Binding Protein C: Defining Function Across Scales Using a Zebrafish Model System.

['FUNDING_R21'] · UNIVERSITY OF VERMONT & ST AGRIC COLLEGE · NIH-10951952

This study is looking at how a protein called MyBP-C affects muscle movement using zebrafish, which helps researchers understand muscle diseases like distal arthrogryposis and find new ways to treat them.

Quick facts

Phase['FUNDING_R21']
Study typeNih_funding
SexAll
SponsorUNIVERSITY OF VERMONT & ST AGRIC COLLEGE (nih funded)
Locations1 site (BURLINGTON, UNITED STATES)
Trial IDNIH-10951952 on ClinicalTrials.gov

What this research studies

This research investigates the role of Myosin-binding protein C (MyBP-C) in muscle contractility by utilizing a zebrafish model. Researchers will employ advanced CRISPR technology to create zebrafish that express specific MyBP-C isoforms, allowing them to study how these proteins influence muscle function and how mutations may lead to conditions like distal arthrogryposis. By observing the effects of these proteins in a living organism, the research aims to provide insights into muscle diseases and potential therapeutic targets.

Who could benefit from this research

Good fit: Ideal candidates for this research are individuals with genetic mutations affecting MyBP-C, particularly those diagnosed with skeletal myopathies such as distal arthrogryposis.

Not a fit: Patients with muscle disorders not linked to MyBP-C mutations or those with unrelated conditions may not benefit from this research.

Why it matters

Potential benefit: If successful, this research could lead to a better understanding of muscle disorders and pave the way for new treatments for patients with skeletal myopathies.

How similar studies have performed: Other research has successfully utilized zebrafish models to study muscle function and genetic mutations, indicating a promising approach for this investigation.

Where this research is happening

BURLINGTON, UNITED STATES

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.

View on NIH RePORTER →

Last reviewed 2026-05-15 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.