How myosin gene and protein changes affect heart and skeletal muscles

Genetics and Molecular Biology of Striated Muscle Myosin

NIH-funded research San Diego State University · NIH-11326263

Researchers are using fruit flies to learn how changes in the myosin motor protein drive aging and inherited heart and skeletal muscle diseases.

Quick facts

Grant typeR37 grant
Study typeNIH-funded research
Funding institutionSan Diego State University NIH-funded
Lab location1 site (San Diego, United States)
Project IDNIH-11326263 on NIH RePORTER

What this research studies

This project uses genetically modified Drosophila (fruit flies) to model human myosin-related muscle diseases and aging. Scientists examine myosin at many levels, from atomic structure and biochemical activity to muscle fiber mechanics, heart function, and fly movement. They test specific myosin residues that are modified during human aging, measure ATPase activity and filament formation, and look for protein aggregates and disrupted proteostasis. The team also tests whether boosting autophagy through FOXO can reduce harmful aggregates in models of inclusion body myopathy type 3 and myosin storage myopathy.

Who could benefit from this research

Good fit: People with inherited myosin-related muscle diseases (for example, inclusion body myopathy type 3 or myosin storage myopathy) or inherited cardiomyopathies linked to myosin abnormalities would be the most relevant patient group for follow-up studies.

Not a fit: People with muscle or heart conditions unrelated to myosin biology, or those seeking immediate clinical treatment, are unlikely to receive direct benefit from these basic fly-model experiments.

Why it matters

Potential benefit: If successful, this work could identify molecular pathways and targets, such as proteostasis or autophagy, that might lead to treatments slowing or preventing muscle degeneration.

How similar studies have performed: Model-organism and cell-based studies have previously highlighted proteostasis and autophagy as promising targets, but translating those findings into proven human therapies is still early and ongoing.

Where this research is happening

San Diego, United States

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.
Last reviewed 2026-06-13 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.