How mitochondria change ribosome RNA and affect genetic disease

New Mechanisms of the Pseudouridine Synthase Module in Mitoribosome Assembly

NIH-funded research State University of New York at Buffalo · NIH-11126638

This project looks at how a mitochondrial enzyme changes ribosomal RNA and how that may matter for people with inherited mitochondrial disorders.

Quick facts

Grant typeNIH-funded research
Study typeNIH-funded research
Funding institutionState University of New York at Buffalo NIH-funded
Lab location1 site (Amherst, United States)
Project IDNIH-11126638 on NIH RePORTER

What this research studies

As someone affected by a mitochondrial condition, it's helpful to know researchers will study a mitochondrial enzyme called RPUSD4 that edits ribosomal RNA. They will use structural biology to visualize the enzyme, genomics to read RNA changes, and biochemistry to test how mutations alter function. The team will examine why certain disease-linked mutations disrupt this RNA modification and how the enzyme recognizes assembling mitochondrial ribosomes. Their combined lab approaches aim to connect molecular changes to patterns seen in mitochondrial genetic diseases.

Who could benefit from this research

Good fit: People with inherited mitochondrial disorders or known mutations affecting mitochondrial rRNA or protein synthesis would be most relevant to this research.

Not a fit: Patients whose conditions do not involve mitochondrial genetic defects or mitochondrial protein synthesis are unlikely to receive direct benefit from this project.

Why it matters

Potential benefit: If successful, this work could explain why some mitochondrial mutations cause disease and suggest new targets for diagnostics or future therapies.

How similar studies have performed: Previous laboratory studies have linked rRNA pseudouridylation to mitochondrial disease, but the precise molecular mechanisms are largely unproven and this project explores new details.

Where this research is happening

Amherst, United States

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.
Conditions DiseaseDisorderGenetic Diseases
Last reviewed 2026-06-13 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.