How a DYT1 gene change affects brain cells in mice

Supplement: Pathophysiology of DYT1 dystonia: Targeted Mouse Models

['FUNDING_R01'] · UNIVERSITY OF FLORIDA · NIH-11232412

Researchers are studying how the common DYT1 gene deletion affects specific brain cells in mice to help people with early-onset DYT1 dystonia.

Quick facts

Phase['FUNDING_R01']
Study typeNih_funding
SexAll
SponsorUNIVERSITY OF FLORIDA (nih funded)
Locations1 site (GAINESVILLE, UNITED STATES)
Trial IDNIH-11232412 on ClinicalTrials.gov

What this research studies

This project uses specially engineered mice that carry the same DYT1/TOR1A mutation found in people. Scientists will turn the mutant gene on or off in particular brain regions and cell types to see which neurons produce dystonia-like signs. The team is focusing on striatal medium spiny neurons because early data point to their important role. By mapping which cells and circuits go wrong, the work aims to point to targets for future treatments.

Who could benefit from this research

Good fit: People with early-onset DYT1 dystonia or family members who carry the DYT1/TOR1A mutation are most likely to benefit from the knowledge this research produces.

Not a fit: People with other forms of dystonia or movement disorders not caused by the DYT1/TOR1A mutation may not receive direct benefit from this work.

Why it matters

Potential benefit: If successful, the findings could identify specific brain-cell targets to guide development of new treatments for DYT1 dystonia.

How similar studies have performed: Previous genetically modified mouse studies have implicated striatal neurons in DYT1 dystonia but have not yet explained how the torsinAΔE mutation causes symptoms, so this work builds on existing animal research rather than testing a proven therapy.

Where this research is happening

GAINESVILLE, UNITED STATES

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.

View on NIH RePORTER →

Last reviewed 2026-05-15 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.