Finding ways to restore protein function in Lowe Syndrome and Dent-2 disease

Restoring Ocrl1 function in Lowe Syndrome and Dent-2 disease

['FUNDING_R01'] · PURDUE UNIVERSITY · NIH-11128743

This project looks for new medicines that can help children with Lowe Syndrome and patients with Dent-2 disease by fixing a problem with a specific protein.

Quick facts

Phase['FUNDING_R01']
Study typeNih_funding
SexAll
SponsorPURDUE UNIVERSITY (nih funded)
Locations1 site (WEST LAFAYETTE, UNITED STATES)
Trial IDNIH-11128743 on ClinicalTrials.gov

What this research studies

Lowe Syndrome and Dent-2 disease are caused by changes in a gene called OCRL1, which leads to a protein that doesn't work correctly. Our team believes that some of these faulty proteins can be made to work again with the right kind of drug. We have already found some promising compounds, including some existing FDA-approved medicines, that can restore the protein's activity in lab tests. This work aims to further test these potential medicines to see if they can help improve the health of those affected by these conditions.

Who could benefit from this research

Good fit: This research is focused on understanding and treating Lowe Syndrome and Dent-2 disease, which primarily affect children and young adults.

Not a fit: Patients without Lowe Syndrome or Dent-2 disease, or those whose condition is not linked to OCRL1 gene mutations, would not directly benefit from this specific research.

Why it matters

Potential benefit: If successful, this work could lead to the first treatments for Lowe Syndrome and Dent-2 disease, potentially improving the lives and extending the lifespan of affected children and patients.

How similar studies have performed: Our lab has identified compounds that restore protein activity in cells, suggesting a promising path forward for this novel approach.

Where this research is happening

WEST LAFAYETTE, UNITED STATES

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.

View on NIH RePORTER →

Last reviewed 2026-05-15 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.