Evaluating a biomarker for assessing gene therapy effectiveness in GM1 gangliosidosis

Validation of analytical methods for quantification of a pentasaccharide biomarker in efficacy assessment of AVV treatment for GM1 gangliosidosis

['FUNDING_U01'] · WASHINGTON UNIVERSITY · NIH-11046644

This study is looking at a special test that measures a sugar in your body fluids to see how well a new gene therapy works for GM1 gangliosidosis, a rare genetic condition, so that doctors can better track treatment progress and help improve your health.

Quick facts

Phase['FUNDING_U01']
Study typeNih_funding
SexAll
SponsorWASHINGTON UNIVERSITY (nih funded)
Locations1 site (SAINT LOUIS, UNITED STATES)
Trial IDNIH-11046644 on ClinicalTrials.gov

What this research studies

This research focuses on GM1 gangliosidosis, a rare genetic disorder caused by a deficiency in the β-galactosidase enzyme. The study aims to validate a specific pentasaccharide biomarker that can be measured in urine, plasma, and cerebrospinal fluid to assess the effectiveness of adeno-associated viral (AAV) gene therapy. By using advanced techniques like liquid chromatography-tandem mass spectrometry, the research seeks to establish a reliable method for evaluating treatment responses in patients. This could help in monitoring the efficacy of new therapies and improving patient outcomes.

Who could benefit from this research

Good fit: Ideal candidates for this research are individuals diagnosed with GM1 gangliosidosis, particularly those who may be eligible for AAV gene therapy.

Not a fit: Patients with other genetic disorders or those not diagnosed with GM1 gangliosidosis may not benefit from this research.

Why it matters

Potential benefit: If successful, this research could lead to better assessment methods for the effectiveness of gene therapies in treating GM1 gangliosidosis, potentially improving patient care.

How similar studies have performed: Previous research has shown promise in using biomarkers for treatment assessment in similar genetic disorders, indicating a potential for success in this approach.

Where this research is happening

SAINT LOUIS, UNITED STATES

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.

View on NIH RePORTER →

Last reviewed 2026-05-15 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.