Ethical guidance for one-person genomic treatments for ultra-rare childhood diseases

Providing ethical guidance for the development of individualized genomic medicine as rare as n-of-1

NIH-funded research Boston Children's Hospital · NIH-11173640

Creating clear ethical guidance to help families and clinicians make choices about individualized gene therapies for children with extremely rare genetic conditions.

Quick facts

Grant typeR01 grant
Study typeNIH-funded research
Funding institutionBoston Children's Hospital NIH-funded
Lab location1 site (Boston, United States)
Project IDNIH-11173640 on NIH RePORTER

What this research studies

This project looks at the ethical, legal, and social questions that come up when doctors design gene-targeted treatments for a single patient, such as customized antisense oligonucleotide (ASO) therapies. Researchers will work with families, clinicians, and ethicists to review real cases, gather perspectives, and identify common concerns like informed consent, therapeutic optimism, and evidence thresholds. They will use those findings to create practical recommendations and documentation that hospitals and families can use when considering n-of-1 treatments. The aim is to make decision-making safer and more transparent for children facing life-threatening rare diseases.

Who could benefit from this research

Good fit: Children with extremely rare genetic disorders (for example, Batten disease) whose care teams are exploring individualized antisense oligonucleotide or similar n-of-1 genomic therapies.

Not a fit: Patients who are seeking standard, approved treatments or who do not have genetic variants amenable to individualized genomic approaches are unlikely to benefit directly from this project.

Why it matters

Potential benefit: If successful, this work could provide clear rules and tools to protect children and guide families and clinicians when considering individualized genomic treatments.

How similar studies have performed: A very small number of individualized ASO cases have shown promise and sparked related ethics work, but comprehensive guidance for n-of-1 genomic medicine remains novel and emerging.

Where this research is happening

Boston, United States

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.
Conditions Batten DiseaseBatten-Mayou DiseaseBatten-Spielmeyer-Vogt Disease
Last reviewed 2026-06-10 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.