ASNA1 gene changes and infant dilated cardiomyopathy

Molecular basis of ASNA1 cardiomyopathy

NIH-funded research University of California, San Diego · NIH-11291819

This work looks at how specific ASNA1 gene changes damage heart muscle cells and cause severe dilated cardiomyopathy in infants.

Quick facts

Grant typeR01 grant
Study typeNIH-funded research
Funding institutionUniversity of California, San Diego NIH-funded
Lab location1 site (La Jolla, United States)
Project IDNIH-11291819 on NIH RePORTER

What this research studies

If my child or I had ASNA1-related heart disease, this research would study why the ASNA1 gene problems break the machinery that places certain proteins into heart cell membranes. The team is using specially engineered mice with heart-specific ASNA1 changes and human stem cell–derived heart cells made from patient cells to see how the mutations affect heart muscle. They are comparing a missense change (V163A) and a null change (C289W,Q305*) alone and together to reproduce the infant disease. The work focuses on the cellular steps that fail so researchers can find points to target for future treatments.

Who could benefit from this research

Good fit: Ideal candidates are infants or family members with known ASNA1 mutations or families affected by early-onset dilated cardiomyopathy who can provide clinical information or biological samples.

Not a fit: People with dilated cardiomyopathy from unrelated genetic causes or common adult-onset heart disease are unlikely to benefit directly from this specific ASNA1-focused work.

Why it matters

Potential benefit: Understanding the molecular cause could point to ways to diagnose, counsel families, and eventually develop targeted treatments for ASNA1-related cardiomyopathy.

How similar studies have performed: The methods—mouse genetic models and human iPSC-derived heart cells—have successfully clarified mechanisms in other rare genetic cardiomyopathies, but applying them to ASNA1 is relatively new.

Where this research is happening

La Jolla, United States

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.
Last reviewed 2026-06-10 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.