A new method for delivering gene editing to treat neurogenetic diseases.

A non-viral CRISPR-mediated genome editing delivery platform as a potential therapy for neurogenetic diseases

NIH-funded research Yale University · NIH-10932377

This study is testing a new way to deliver gene editing treatments directly into the spinal fluid to help people with neurogenetic diseases like Angelman syndrome and H1-4 syndrome, aiming to fix a key gene that isn't working properly.

Quick facts

Grant typeNIH-funded research
Study typeNIH-funded research
Funding institutionYale University NIH-funded
Lab location1 site (New Haven, United States)
Project IDNIH-10932377 on NIH RePORTER

What this research studies

This research focuses on developing a safe and effective delivery system for CRISPR-based gene editing specifically targeting neurogenetic diseases like Angelman syndrome and H1-4 syndrome. The approach utilizes a chemically modified ribonucleoprotein (cRNP) that can be administered directly into the spinal fluid, allowing it to reach neuronal cells in the brain. By reducing the expression of a specific antisense RNA, the therapy aims to restore the function of a critical gene involved in these disorders. This innovative method seeks to overcome the challenges of traditional gene therapy delivery.

Who could benefit from this research

Good fit: Ideal candidates for this research include children and adults diagnosed with Angelman syndrome or H1-4 syndrome.

Not a fit: Patients with neurogenetic disorders not related to Angelman syndrome or H1-4 syndrome may not benefit from this research.

Why it matters

Potential benefit: If successful, this research could provide a groundbreaking treatment option for patients with severe neurogenetic disorders, potentially improving their neurological function and quality of life.

How similar studies have performed: Previous research has shown promise in using CRISPR and antisense oligonucleotides for similar genetic conditions, indicating a potential for success with this novel delivery approach.

Where this research is happening

New Haven, United States

Researchers

About this research

  1. This is an active NIH-funded research project — typically early-stage science, not a clinical trial accepting patient enrollment.
  2. Some NIH-funded labs run parallel clinical studies or seek volunteers for related work. To check, contact the principal investigator or institution listed above.
  3. For full project details, budget, and progress reports, visit the official NIH RePORTER page below.
Conditions Angelman Syndrome
Last reviewed 2026-06-13 by the Find a Trial editorial team. Information on this page is for educational purposes and is not medical advice. Always consult qualified healthcare professionals about clinical trial participation.